<?xml version="1.0" encoding="utf-8"?>
<!DOCTYPE article PUBLIC "-//NLM//DTD JATS (Z39.96) Journal Publishing DTD v1.0 20120330//EN" "JATS-journalpublishing1.dtd">

<article article-type="research-article" dtd-version="1.0" xml:lang="ko" xmlns:mml="http://www.w3.org/1998/Math/MathML" xmlns:xlink="http://www.w3.org/1999/xlink" xmlns:xsi="http://www.w3.org/2001/XMLSchema-instance">
<front>
<journal-meta>
<journal-id journal-id-type="publisher-id">KJM</journal-id>
<journal-title-group>
<journal-title>The Korean Journal of Medicine</journal-title><abbrev-journal-title>Korean J Med</abbrev-journal-title></journal-title-group>
<issn pub-type="ppub">1738-9364</issn>
<issn pub-type="epub"></issn>
<publisher>
<publisher-name>The Korean Journal of Medicine</publisher-name></publisher></journal-meta>
<article-meta>
<article-id pub-id-type="doi">10.3904/kjm.2012.82.4.432</article-id>
<article-id pub-id-type="publisher-id">kjm-82-4-432-7</article-id>
<article-categories>
<subj-group>
<subject>임상화보</subject>
</subj-group>
<subj-group xml:lang="en">
<subject>Images in Medicine</subject>
</subj-group>
</article-categories>

<title-group>
<article-title>농양으로 오인된 횡문근육 림프종</article-title>
<trans-title-group>
<trans-title xml:lang="en">Skeletal Muscle Lymphoma Mimicking Abscess</trans-title>
</trans-title-group>
</title-group>

<contrib-group>
<contrib contrib-type="author">
<name-alternatives>
<name name-style="western" xml:lang="en"><surname>Lim</surname><given-names>Do Hyoung</given-names></name>
<name name-style="eastern" xml:lang="ko"><surname>임</surname><given-names>도형</given-names></name>
</name-alternatives>
<xref ref-type="corresp" rid="c1-kjm-82-4-432-7"/>
</contrib>
<contrib contrib-type="author">
<name-alternatives>
<name name-style="western" xml:lang="en"><surname>Lee</surname><given-names>Soon Il</given-names></name>
<name name-style="eastern" xml:lang="ko"><surname>이</surname><given-names>순일</given-names></name>
</name-alternatives>
</contrib>
<contrib contrib-type="author">
<name-alternatives>
<name name-style="western" xml:lang="en"><surname>Park</surname><given-names>Keon Woo</given-names></name>
<name name-style="eastern" xml:lang="ko"><surname>박</surname><given-names>건우</given-names></name>
</name-alternatives>
</contrib>

<aff-alternatives id="af1-kjm-82-4-432-7">
<aff xml:lang="en">Department of Internal Medicine, Dankook University Hospital, Cheonan, <country>Korea</country></aff>
<aff xml:lang="ko">단국대학교병원 내과학교실</aff>
</aff-alternatives>
</contrib-group>

<author-notes>
<corresp id="c1-kjm-82-4-432-7" xml:lang="en">Correspondence to Do Hyoung Lim, M.D. &#x02003; Department of Internal Medicine, Dankook University Hospital, 201 Manghyang-ro, Dongnam-gu, Cheonan 330-715, Korea &#x02003; Tel: +82-41-550-3294, Fax: +82-41-550-7058, E-mail: <email>dos143@paran.com</email></corresp>
</author-notes>

<pub-date pub-type="ppub">
<day>1</day>
<month>4</month>
<year>2012</year></pub-date>

<pub-date pub-type="epub">
<day>1</day>
<month>4</month>
<year>2012</year></pub-date>

<volume>82</volume>
<issue>4</issue>
<fpage>432</fpage>
<lpage>434</lpage>
<permissions>
<copyright-statement xml:lang="en">Copyright &#x024d2; 2012 The Korean Association of Internal Medicine</copyright-statement>
<copyright-year>2012</copyright-year>
<license xml:lang="en">
<license-p>This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (<ext-link ext-link-type="uri" xlink:href="http://creativecommons.org/licenses/by-nc/3.0/">http://creativecommons.org/licenses/by-nc/3.0/</ext-link>) which permits unrestricted noncommercial use, distribution, and reproduction in any medium, provided the original work is properly cited.</license-p></license></permissions>

<kwd-group xml:lang="ko">
<kwd>횡문근 림프종</kwd>
<kwd>이형성 거대 세포 림프종</kwd>
<kwd>비호지킨 림프종</kwd>
</kwd-group>
<kwd-group xml:lang="en">
<kwd>Skeletal muscle lymphoma</kwd>
<kwd>Anaplastic large cell lymphoma</kwd>
<kwd>Non-Hodgkin&#x02019;s lymphoma</kwd>
</kwd-group></article-meta></front>



<body>
<p>32세 남자 환자가 3-4주 전부터 발생한 전신 무력감 및 피로감을 주소로 내원하였다. 환자는 과거력상 특이소견 없었으며, 최근 한 달간 약 5 kg의 체중감소와 열감 등이 동반되었고 외부병원에서 시행한 혈액검사상 간기능 검사 이상소견이 보여 본원으로 전원되었다. 입원 후 시행한 신체검사상 체온이 40.1&#x02103;까지 증가하였고, 혈액검사상 총 백혈구 4,030/&#x000b5;L (호중구: 61.1&#x0025;, 림프구: 29.0&#x0025;), 혈색소 14.6 g/dL, 혈소판 148 &#x000d7; 10<sup>3</sup>/&#x000b5;L, AST/ALT/T-Bilirubin은 162/76/0.67, CK/LDH 2919/1347, CRP 1.51 mg/dL로 각각 확인되었다. 환자는 복부-골반 전산화 단층 촬영술을 시행하였고, 우측 중둔근에 약 2.2 &#x000d7; 5.8 cm 크기의 경계면 조영 증강이 되는 병변이 발견되었고, 근육 내 농양이 가장 의심되었다(<xref rid="f1-kjm-82-4-432-7" ref-type="fig">Fig. 1</xref>). 그러나 농양의 발생 위치가 드문 곳이고, 젊고 건강한 남자에서 발생한 점 등이 비 특이적이라고 판단되어, 경험적 항생제 치료를 시작하면서 자기공명영상을 추가로 확인하였다. 골반 자기공명영상에서 주위 근막과 근육 사이 지방층 및 피하지방층을 간질성으로 침투하는 약 6.5 cm 크기의 농양으로 의심되는 병변이 우측 중둔근에서 역시 관찰되었다(<xref rid="f2-kjm-82-4-432-7" ref-type="fig">Fig. 2</xref>). 환자는 초음파하 세침흡인조직 검사를 시행하였고, 병리 검사상에서 ALK 음성인 이형성 거대 세포 림프종이 진단되었다. 이후 병기 설정을 위해 시행한 양전자 단층 촬영상에서도 이전과 같은 부위에 과 대사성병변이 관찰되었으며(<xref rid="f3-kjm-82-4-432-7" ref-type="fig">Fig. 3</xref>), 우측 이두근 및 양측 장요근에도 림프종의 침범이 관찰되었다. 그렇지만 신체검사 및 양전자 단층 촬영상에서 의미 있는 림프절 종대는 관찰되지 않았다. 환자는 4기 이형성 거대 세포 림프종 진단하에 정자 냉동보관 및 항암화학요법을 준비 중이다.</p>
<p>악성 림프종은 림프조직을 포함하는 어느 부위나 침범이 가능하지만 횡문근을 일차적으로 침범하는 악성 림프종은 매우 드문 것으로 보고되고 있다[<xref ref-type="bibr" rid="b1-kjm-82-4-432-7">1</xref>,<xref ref-type="bibr" rid="b2-kjm-82-4-432-7">2</xref>]. 림프종의 근육침범은 종괴나 근육종창[<xref ref-type="bibr" rid="b3-kjm-82-4-432-7">3</xref>] 등의 형태로 나타날 수 있고, 드물게는 특이소견 없이 부검에서만 발견되는 경우도 있으며[<xref ref-type="bibr" rid="b4-kjm-82-4-432-7">4</xref>], 이 환자의 경우에서처럼 감염으로 오인되는 경우도 있다[<xref ref-type="bibr" rid="b5-kjm-82-4-432-7">5</xref>]. 또한 비 전형적인 임상양상을 보이는 근육 농양의 경우 다른 악성 질환이나 결핵, 기생충 감염 등을 보고하기도 하였다[<xref ref-type="bibr" rid="b6-kjm-82-4-432-7">6</xref>-<xref ref-type="bibr" rid="b8-kjm-82-4-432-7">8</xref>]. 따라서 비 특이적인 근육의 염증소견이 보일 때에는 반드시 미생물학적 검사 및 조직학적 진단이 필요할 것으로 생각된다.</p></body>



<back>



<ref-list xml:lang="en">
<title>REFERENCES</title>

<ref id="b1-kjm-82-4-432-7">
<label>1</label>
<element-citation publication-type="journal">
<person-group person-group-type="author">
<name><surname>Travis</surname><given-names>WD</given-names></name>
<name><surname>Banks</surname><given-names>PM</given-names></name>
<name><surname>Reiman</surname><given-names>HM</given-names></name>
</person-group>
<article-title>Primary extranodal soft tissue lymphoma of the extremities</article-title>
<source>Am J Surg Pathol</source>
<year>1987</year>
<volume>11</volume>
<fpage>359</fpage>
<lpage>366</lpage>
</element-citation></ref>


<ref id="b2-kjm-82-4-432-7">
<label>2</label>
<element-citation publication-type="journal">
<person-group person-group-type="author">
<name><surname>Zucca</surname><given-names>E</given-names></name>
<name><surname>Roggero</surname><given-names>E</given-names></name>
<name><surname>Bertoni</surname><given-names>F</given-names></name>
<name><surname>Cavalli</surname><given-names>F</given-names></name>
</person-group>
<article-title>Primary extranodal non-Hodgkin&#x0027;s lymphomas. Part 1: Gastrointestinal, cutaneous and genitourinary lymphomas</article-title>
<source>Ann Oncol</source>
<year>1997</year>
<volume>8</volume>
<fpage>727</fpage>
<lpage>737</lpage>
</element-citation></ref>


<ref id="b3-kjm-82-4-432-7">
<label>3</label>
<element-citation publication-type="journal">
<person-group person-group-type="author">
<name><surname>Choudhury</surname><given-names>J</given-names></name>
<name><surname>Yalamanchil</surname><given-names>M</given-names></name>
<name><surname>Friedenberg</surname><given-names>W</given-names></name>
</person-group>
<article-title>Skeletal muscle lymphoma</article-title>
<source>Med Oncol</source>
<year>2002</year>
<volume>19</volume>
<fpage>125</fpage>
<lpage>129</lpage>
</element-citation></ref>


<ref id="b4-kjm-82-4-432-7">
<label>4</label>
<element-citation publication-type="journal">
<person-group person-group-type="author">
<name><surname>Buerger</surname><given-names>LF</given-names></name>
<name><surname>Monteleone</surname><given-names>PN</given-names></name>
</person-group>
<article-title>Leukemic-lymphomatous infiltration of skeletal muscle. Systematic study of 82 autopsy cases</article-title>
<source>Cancer</source>
<year>1966</year>
<volume>19</volume>
<fpage>1416</fpage>
<lpage>1422</lpage>
</element-citation></ref>


<ref id="b5-kjm-82-4-432-7">
<label>5</label>
<element-citation publication-type="journal">
<person-group person-group-type="author">
<name><surname>Baddour</surname><given-names>LM</given-names></name>
<name><surname>Haden</surname><given-names>KH</given-names></name>
<name><surname>Allen</surname><given-names>JW</given-names></name>
</person-group>
<article-title>Primary skeletal muscle lymphoma presenting as refractory cellulitis</article-title>
<source>Cutis</source>
<year>2001</year>
<volume>68</volume>
<fpage>223</fpage>
<lpage>226</lpage>
</element-citation></ref>


<ref id="b6-kjm-82-4-432-7">
<label>6</label>
<element-citation publication-type="journal">
<person-group person-group-type="author">
<name><surname>Toda</surname><given-names>K</given-names></name>
<name><surname>Yasunaga</surname><given-names>Y</given-names></name>
<name><surname>Takemoto</surname><given-names>S</given-names></name>
<name><surname>Terada</surname><given-names>Y</given-names></name>
</person-group>
<article-title>MR image and CT scan of a tuberculous abscess in the gluteus maximus muscle</article-title>
<source>Comput Med Imaging Graph</source>
<year>1998</year>
<volume>22</volume>
<fpage>425</fpage>
<lpage>427</lpage>
</element-citation></ref>


<ref id="b7-kjm-82-4-432-7">
<label>7</label>
<element-citation publication-type="journal">
<person-group person-group-type="author">
<name><surname>Bar-Dayan</surname><given-names>Y</given-names></name>
<name><surname>Fishman</surname><given-names>A</given-names></name>
<name><surname>Levi</surname><given-names>Z</given-names></name>
<name><surname>Rachmani</surname><given-names>R</given-names></name>
</person-group>
<article-title>Squamous cell carcinoma of the cervix with psoas abscess-like metastasis in an HIV-negative patient</article-title>
<source>Isr J Med Sci</source>
<year>1997</year>
<volume>33</volume>
<fpage>674</fpage>
<lpage>676</lpage>
</element-citation></ref>


<ref id="b8-kjm-82-4-432-7">
<label>8</label>
<element-citation publication-type="journal">
<person-group person-group-type="author">
<name><surname>Lambertucci</surname><given-names>JR</given-names></name>
<name><surname>Rayes</surname><given-names>AA</given-names></name>
<name><surname>Serufo</surname><given-names>JC</given-names></name>
<name><surname>Nobre</surname><given-names>V</given-names></name>
</person-group>
<article-title>Pyogenic abscesses and parasitic diseases</article-title>
<source>Rev Inst Med Trop Sao Paulo</source>
<year>2001</year>
<volume>43</volume>
<fpage>67</fpage>
<lpage>74</lpage>
</element-citation></ref>

</ref-list>

<sec sec-type="display-objects" xml:lang="en">
		<title>Figures</title>

<fig id="f1-kjm-82-4-432-7" position="float">
		<label>Figure 1.</label><caption><p>A-P CT scan of the patient showed that about 2.2 &#x00d7; 5.8 cm sized rim-enhancing lesion in right gluteus medius muscle. Which was considered as abscess, initially.</p></caption>
		<graphic xlink:href="kjm-82-4-432-7f1.tif"/></fig>

<fig id="f2-kjm-82-4-432-7" position="float">
		<label>Figure 2.</label><caption><p>Pelvis MRI of the patient showed that about 6.5 cm extent abscess in right gluteus medius. Which had interstitial infiltration in the adjacent fascia, intermuscular and subcutaneous fat layer (Left-contrast-enhanced T1-weighted image, right-T2-weighted fast spin-echo image).</p></caption>
		<graphic xlink:href="kjm-82-4-432-7f2.tif"/></fig>

<fig id="f3-kjm-82-4-432-7" position="float">
		<label>Figure 3.</label><caption><p>PET/CT scan of the patient showed lobulating hypermetabolic lesion in right gluteus medius (SUVmax 9.1).</p></caption>
		<graphic xlink:href="kjm-82-4-432-7f3.tif"/></fig>

</sec>
</back></article>