A Case of Diffuse Idiopathic Skeletal Hyperostosis Presenting with Dysphagia
Secondary to Cervical Osteophyte and Restrictive Ventilatory Impairment |
Hong Jik Lee, Ji Hyun Lee, Min Jeong Kim, Ki Sup Byun, Hyun Jung Yeo, Ho Joon Im, Kyoung Sik Nam |
Division of Rheumatology, Department of Internal Medicine, Maryknoll Medical Center, Busan, Korea |
미만특발골격뼈과다증 환자에서 경추부 골극에 의한 삼킴곤란 및
제한성 환기장애가 동시에 발생한 1예 |
이홍직, 이지현, 김민정, 변기섭, 여현정, 임호준, 남경식 |
메리놀병원 류마티스내과 |
Correspondence:
Ji Hyun Lee, Tel: +82-51-461-2469, Fax: +82-51-441-6950, Email: ete@lycos.co.kr |
Received: 25 June 2013 • Revised: 4 October 2013 • Accepted: 28 October 2013 |
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This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/3.0/) which permits
unrestricted noncommercial use, distribution, and reproduction in any medium, provided the original work is properly cited. |
Abstract |
Diffuse idiopathic skeletal hyperostosis (DISH) is a condition characterized by the calcification and ossification of soft tissue,
and can lead to severe cervical kyphosis, presenting with a spectrum of physical complaints including dysphagia, hoarseness,
stridor, aspiration pneumonia, and dyspnea due to airway compromise. Restrictive ventilatory impairment is very rare. We
encountered a 73-year-old man with DISH presenting with progressive dysphagia and dyspnea over a few months. The symptoms
were evaluated with a video fluoroscopy swallowing study and pulmonary function tests (PFT). The PFT revealed restrictive
ventilatory impairment. A neck magnetic resonance imaging (MRI) study showed anterior cervical osteophytes causing upper
airway compromise and compression of the esophagus. Osteophytes were removed surgically and the patient improved clinically.
Here, we describe the case with a literature review. |
Key Words:
Diffuse idiopathic skeletal hyperostosis; Dysphagia; Osteophyte; Cervical; Restrictive ventilatory impairment |
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